A case of paroxysmal kinesigenic dyskinesia with spastic paraparesis

Y. Ohta; Yasuhiro Manabe; C. Sasaki; M. Shiote; T. Hayashi; M. Shoji; K. Abe

doi:10.1179/016164102101200582

A case of paroxysmal kinesigenic dyskinesia with spastic paraparesis

Y. Ohta, Yasuhiro Manabe, C. Sasaki, M. Shiote, T. Hayashi, M. Shoji, K. Abe

Research output: Contribution to journal › Article › peer-review

Abstract

We report the first case of paroxysmal kinesigenic dyskinesia (PKD) with spastic paraparesis. A 17-year-old male began to show a dystonic posture in both his upper limbs when walking at age 12 years. Neurological examination revealed bilateral talipes cavus, spasticity in all extremities with general hyperreflexia and pathological reflexes. On starting to walk, he showed a dystonic posture in bilateral maniphalanx, wrists, elbows, and toes. Magnetic resonance imaging (MRI) revealed high T2-weighted signal intensity in bilateral pyramidal tract. Although the combination of pyramidal and the basal ganglia disorders is very rare, the present case suggests an inter-relation of the pyramidal and the basal ganglia systems.

Original language	English
Pages (from-to)	684-686
Number of pages	3
Journal	Neurological Research
Volume	24
Issue number	7
DOIs	https://doi.org/10.1179/016164102101200582
Publication status	Published - Oct 2002

Keywords

Paroxysmal kinesigenic dyskinesia
Spastic paraparesis

ASJC Scopus subject areas

Neurology
Clinical Neurology

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10.1179/016164102101200582

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abstract = "We report the first case of paroxysmal kinesigenic dyskinesia (PKD) with spastic paraparesis. A 17-year-old male began to show a dystonic posture in both his upper limbs when walking at age 12 years. Neurological examination revealed bilateral talipes cavus, spasticity in all extremities with general hyperreflexia and pathological reflexes. On starting to walk, he showed a dystonic posture in bilateral maniphalanx, wrists, elbows, and toes. Magnetic resonance imaging (MRI) revealed high T2-weighted signal intensity in bilateral pyramidal tract. Although the combination of pyramidal and the basal ganglia disorders is very rare, the present case suggests an inter-relation of the pyramidal and the basal ganglia systems.",

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AU - Ohta, Y.

AU - Manabe, Yasuhiro

AU - Sasaki, C.

AU - Shiote, M.

AU - Hayashi, T.

AU - Shoji, M.

AU - Abe, K.

PY - 2002/10

Y1 - 2002/10

N2 - We report the first case of paroxysmal kinesigenic dyskinesia (PKD) with spastic paraparesis. A 17-year-old male began to show a dystonic posture in both his upper limbs when walking at age 12 years. Neurological examination revealed bilateral talipes cavus, spasticity in all extremities with general hyperreflexia and pathological reflexes. On starting to walk, he showed a dystonic posture in bilateral maniphalanx, wrists, elbows, and toes. Magnetic resonance imaging (MRI) revealed high T2-weighted signal intensity in bilateral pyramidal tract. Although the combination of pyramidal and the basal ganglia disorders is very rare, the present case suggests an inter-relation of the pyramidal and the basal ganglia systems.

AB - We report the first case of paroxysmal kinesigenic dyskinesia (PKD) with spastic paraparesis. A 17-year-old male began to show a dystonic posture in both his upper limbs when walking at age 12 years. Neurological examination revealed bilateral talipes cavus, spasticity in all extremities with general hyperreflexia and pathological reflexes. On starting to walk, he showed a dystonic posture in bilateral maniphalanx, wrists, elbows, and toes. Magnetic resonance imaging (MRI) revealed high T2-weighted signal intensity in bilateral pyramidal tract. Although the combination of pyramidal and the basal ganglia disorders is very rare, the present case suggests an inter-relation of the pyramidal and the basal ganglia systems.

KW - Paroxysmal kinesigenic dyskinesia

KW - Spastic paraparesis

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A case of paroxysmal kinesigenic dyskinesia with spastic paraparesis

Abstract

Keywords

ASJC Scopus subject areas

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